A previously well 43-yr-old man with congenital hypospadias presented
with a fungating lesion of 2 mths duration and surrounding the ventral
urethral opening. After biopsy showed this to be a squamous cell carc
inoma, a definitive procedure of partial penile amputation and urethro
plasty was performed. This is believed to be the first reported case o
f squamous cell carcinoma of the distal urethra in conjunction with hy
pospadias.