We report a patient with an anorectal malformation and an abnormal pen
is with an isolated prepuce, double glans, and two corpora cavernosa.
A right main urethra opened into the bladder neck; the right meatus wa
s hypospadiac. The proximal end of the left accessory urethra opened i
nto the right prostatic urethra and the left meatus was orthotopic. Se
vere chordee and normal urinary flow through both meatuses were presen
t. At the age of 4 years, the diphallus was corrected. Both corpora ca
vernosa were dissected and the urethra was reconstructed, lengthening
the right urethra with a 2.5-cm fragment of left urethra as a free gra
ft excised from the emergence point and joined to the main urethra pas
teriorly. The right urethra, whose meatus was hypospadiac and lateral,
was dissected until a medial course was obtained. Tile glans was reco
nstructed using the lateral aspect of each glans; both medial aspects
were extirpated. To correct the urethral trajectory, the urethra was f
ixed to the tip of the glans. A penis with two corpora Cavernosa, a si
ngle glans, and a complete urethra with a meatus at the tip of the gla
ns was obtained. The prepuce was reconstructed from the dorsal redunda
nt aspect. The postoperative course was satisfactory.