Three unique cases of urethral duplication, often referred to as conge
nital posterior urethral perineal fistulae, are presented. Presenting
signs and symptoms, evaluation, and treatment are discussed, and the l
iterature is reviewed. Although labeled as a fistula in the literature
, this entity most likely represents a distinct type of urethral dupli
cation. A functional dorsal urethra separates it from the other forms
of urethral duplication.