PURPOSE: We studied a case of chronic papilledema in a 5-year-old chil
d with visual loss who presented no obvious cosmetic abnormalities, ME
THODS: Neuroradiologic investigations were suggestive of craniosynosto
sis, The child underwent decompressive cranial surgery. Postoperativel
y, the papilledema totally regressed, and visual acuity recovered to 2
0/20 in both eyes, RESULTS: The chronic papilledema was confirmed to b
e related to harmonious oxycephaly. CONCLUSION: Insidious craniosynost
osis is an unusual cause of chronic papilledema in childhood. The papi
lledema may be resolved and visual loss prevented by surgery.