OBJECTIVE AND IMPORTANCE: Primary hydatid cysts of the spinal canal ar
e very rare. The patient in the present case presented with lower caud
a equina compression caused by a primary solitary hydatid cyst of the
sacral spinal canal, which is a remote possibility. To the best of our
knowledge, such a case has not been reported previously. CLINICAL PRE
SENTATION: A 15-year-old male patient presented with lower motor neuro
ne type of bladder and bowel involvement, with saddle-shaped anesthesi
a involving S2-S5 dermatomes. Plain x-rays and magnetic resonance imag
ing (MRI) scans revealed a widened sacral canal with pressure changes.
MRI scans confirmed the cystic nature of the lesion, which had no spe
cific characteristics and demonstrated intensities that were similar t
o those of cerebrospinal fluid. TECHNIQUE: Surgical exploration of the
sacral canal with enucleation of the cyst in tote was performed. A mi
dline posterior approach was used by decompressing thinned posterior e
lements. Adjuvant therapy with mebendazole or albendazole was not admi
nistered, although recently, some authors claim good results with inte
grated surgical and medical treatment. CONCLUSION: The patient experie
nced dramatic improvement and became continent. At a follow-up examina
tion after 1 year, he had only minimal urinary stress incontinence. If
spinal hydatid cyst is surgically removed unruptured and other common
primary sites are excluded, medical treatment can be deferred, provid
ed the patient undergoes strict follow-up. MRI, although not specific
for hydatid disease, should be the investigation of choice in suspecte
d cases of spinal hydatid cyst.