Stridor implies partial airway obstruction, resulting from intrinsic o
r extrinsic abnormalities of the upper respiratory tract. In a neonate
whose airway is small, soft and easily occluded this may be potential
ly life threatening. Its immediate diagnosis with prompt therapy is a
rewarding challenge. When stridor occurs in a neonate with congenital
hypothyroidism, surgically amenable cause of obstruction due to an ect
opic thyroid or thyroglossal cyst has to be seriously considered. We r
eport a case of neonatal stridor caused by a lingual thyroid, and disc
uss the imaging approach.