OBJECTIVE AND IMPORTANCE: We report the case of a woman presenting wit
h sudden neurological deficit, revealing a parasellar dermoid cyst. To
our knowledge, this clinicopathological finding is the first reported
in the literature. CLINICAL PRESENTATION: A neurological examination
of the patient revealed a left hemiparesis, including central facial p
alsy, which hampered her speech, The well-documented neuroradiological
work-up (including computed tomography, magnetic resonance imaging, a
nd magnetic resonance angiography) demonstrated right frontorolandic i
schemia caused by a right supra-and parasellar dermoid cyst leading to
middle and anterior cerebral arterial stenoses, INTERVENTION: Surgica
l intervention, using a right subfrontopterional approach, was success
ful. Complete dermoid cyst removal was achieved. The mechanism of the
arterial stenoses is extensively discussed and is thought to result fr
om an inflammatory reaction of the basal vessels, CONCLUSION: The pati
ent recovered fully. Nevertheless, postoperative magnetic resonance im
aging confirmed cerebral infarction.