Midline upper lip sinuses alone are rare entities, with less than 25 c
ases reported previously. Midline upper lip sinuses with associated cl
eft lip are even more rare. A patient report of median cleft lip with
associated upper lip sinuses in a 16-year-old boy is presented. Contro
versy exists as to whether these abnormalities are related. This repor
t demonstrates the plausibility of a cause-and-effect relationship bet
ween midline clefts and sinuses.