A highly atypical case of osteoid osteoma of L1 is reported. The patient pr
esented with severe spinal stiffness and bilateral alternating pain in the
upper part of the buttocks extremely responsive tb nonsteroidal antiinflamm
atory therapy. There was-no scoliosis. The first diagnosis considered was a
nkylosing spondylitis, although plain films of the spine and sacroiliac joi
nts were normal.-Careful analysis of physical findings with routine examina
tion for painful spinal stiffness with or without the classical spinal scol
iosis is essential to the diagnosis of osteoid osteoma. When plain radiogra
phs are normal, as is often the case, whole body radionuclide bone scanning
is valuable for identifying the site of this benign tumor, which can then
be further investigated using other imaging techniques.