Atypical and typical cranial dystonia following dental procedures

It is generally recognized that focal dystonia of the limbs or cervical reg ion and blepharospasm sometimes follow, and in these cases may be caused or triggered by, peripheral injury. However, the association between peripher al injury and lower cranial dystonia is rare. We report eight cases who dev eloped cranial dystonia within hours to months following a dental procedure . One group of five cases, all women, developed atypical dystonia associate d with painful paresthesias at the site of dystonia. Two of these five case s had fixed jaw-deviating dystonia, whereas the remaining three had additio nal tremor and spread of their dystonia to involve the tongue in all three, and the lips and neck in two cases. These five patients are reminiscent of cases of limb causalgia-dystonia syndrome, which occurs after minor periph eral trauma and can spread. The remaining three cases developed more typica l cranial dystonia following the dental procedure. There was no family hist ory of dystonia or prior use of neuroleptics in any of the patients. The cl ose association in time and location of the procedure and onset of symptoms suggests that the onset of the dystonia may have been caused by the dental intervention, but whether there is a causal relationship between the denta l intervention and the development of the dyskinesias requires further epid emiologic studies.