Haemopneumothorax from congenital cystic adenomatoid malformation in a cryptorchidism patient

Citation
Sc. Lee et al., Haemopneumothorax from congenital cystic adenomatoid malformation in a cryptorchidism patient, EUR RESP J, 15(2), 2000, pp. 430-432
Citations number
11
Categorie Soggetti
Cardiovascular & Respiratory Systems","da verificare
Journal title
EUROPEAN RESPIRATORY JOURNAL
ISSN journal
09031936 → ACNP
Volume
15
Issue
2
Year of publication
2000
Pages
430 - 432
Database
ISI
SICI code
0903-1936(200002)15:2<430:HFCCAM>2.0.ZU;2-7
Abstract
Congenital cystic adenomatoid malformation (CCAM) of the lung is an uncommo n congenital anomaly, especially in young adults. This study reports an 18- yr-old male with CCAM I involving the right upper lobe, who presented with a moderate spontaneous haemopneumothorax initially. The patient also had bi lateral abdominal cryptorchidism which required surgical treatment earlier in childhood. The chest radiographs and contrast-enhanced computed tomograp hic scan of the chest shelved a multicystic lesion with air-fluid levels in the right upper lung. The right upper lobe was resected through a posterol ateral thoracotomy. Histological examination confirmed the diagnosis of CCA M. To the authors' knowledge, congenital cystic adenomatoid malformation prese nting with spontaneous haemopneumothorax and haemoptysis has never been des cribed in the literature.