Idiopathic ocular neuromyotonia: a neurovascular compression syndrome?

Ocular neuromyotonia in the muscles innervated by the right oculomotor nerv e was diagnosed in a patient without a history of radiation therapy. Electr omyography of the levator palpebrae showed continuous motor unit activity. Brain MRI disclosed a close contact between the right third cranial nerve a nd a basilar artery dolichoectasia. The patient partly benefited from carba mazepine therapy. This unique finding suggests that neurovascular compressi on syndrome could be an hitherto unrecognised cause of ocular neuromyotonia .