Objective: "La maladie de Grisel" (Grisel's syndrome) is a spontaneously oc
curring atlantoaxial subluxation with torticollis. We present a case of atl
antoaxial subluxation occurring in a 20-year period of pharyngoplasty surge
ry. The occurrence of a "spontaneous" atlantoaxial subluxation after oral c
avity or pharynx operations is rare. Because some neck pain and stiffness a
re commonly seen after these kinds of operations, we would like to draw att
ention to this unusual complication, Symptoms associated with a torticollis
after an operation in the oral cavity or pharynx requires additional inves
tigation to exclude this rare complication, A review of the available liter
ature concerning etiology and treatment of la maladie de Grisel is presente
d.