Cutis marmorata telangiectatica congenita (CMTC) is an uncommon sporadic co
ngenital vascular anomaly. Of the 111 patients with CMTC examined in our cl
inic during the past 25 years, 4 were found to have hypospadias. All cases
were sporadic. Although CMTC has been associated with various abnormalities
, to our knowledge there are no reports in the literature of concurrent hyp
ospadias.